Dieulafoy's disease of the bronchus: report of a case and review of the literature.

ABSTRACT:

Background

Dieulafoy's disease is a vascular anomaly characterized by the presence of a tortuous dysplastic artery in the submucosa. Although frequently occurring in the gastrointestinal tract, multiple cases of Dieulafoy's disease in the bronchus have been reported in the literature.

Methods and results

We report a case of a 15-year-old boy suffering recurrent massive hemoptysis. Bilobectomy stopped bleeding after unsuccessful treatment with embolization of bronchial artery.

Conclusion

It is concluded a congenital origin of this disease. Angiography and endobronchial ultrasonography can be used to diagnose Dieulafoy's disease of bronchus whereas bronchoscopy biopsy should be avoided. Surgery is needed when embolization fails.

SUBMITTER: Fang Y 

PROVIDER: S-EPMC4263116 | biostudies-literature | 2014 Dec

REPOSITORIES: biostudies-literature